Endoscopic dacryocystorhinostomy as an option management of syndrome- related congenital dacryocystocele: a case report

https://doi.org/10.19106/JMedSci005304202110

Yunia Irawati(1*), Alexander Krishna Ernanda(2), Florentina Priscilia(3), Retno Sulistyo Wardani(4)

(1) Plastic and Reconstructive Surgery Division, Department of Ophthalmology, Faculty of Medicine, Universitas Indonesia/Dr. Cipto Mangunkusumo Hospital, Jakarta
(2) Resident of Department of Ophthalmology, Faculty of Medicine, Universitas Indonesia/Dr. Cipto Mangunkusumo Hospital, Jakarta
(3) Research Assistant, Department of Ophthalmology, Facutly of Medicine, Universitas Indonesia/Dr. Cipto Mangunkusumo Hospital, Jakarta, Indonesia
(4) Rhinology Division, Department of Ear Nose Throat, Faculty of Medicine, Universitas Indonesia/Dr. Cipto Mangunkusumo Hospital, Jakarta
(*) Corresponding Author

Abstract


Congenital dacryocystocele (CD) is a rare anomaly of the medial region of the orbit, caused by distal at the level of the valve of Hasner and proximal at the level of the valve of Rosenmuller obstruction of the lacrimal system. It may present as isolated abnormalities or maybe associated with syndromes. We described a neonate with a history of bilateral enlarged lacrimal sacs below medial canthal tendon with blue-grayish color and epiphora.  Computed tomography (CT) scan resulted in congenital dacryocystocele. She was given topical antibiotics and Crigler massage as conservative treatment. In the first week, the right eye got a complete resolution. Otherwise, the left eye’s lesion was worsening. The patient underwent endoscopic dacryocystorhinostomy (En-DCR) and silicone intubation on the left eye. Epiphora resolved with no recurrence at one month follow up. Conservative treatment and En-DCR have a success rate with no complication and widely used nowadays. In the case of CD associated with a syndrome, multidiscipline workups and treatment are essential.


Keywords


congenital dacryocystocele; epiphora; endoscopic dacryocystorhinostomy; syndrome

Full Text:

PDF


References


  1. Lueder GT. The association of neonatal dacryocystoceles and infantile dacryocystocele with nasolacrimal duct cysts. Trans Am Ophthalmol Soc 2012; 110:74-93.
  2. Zhang Y, Fan Y, Fan J, Cui Y. Selection of surgical intervention for congenital dacryocystocele. Eur J Ophthalmol 2019; 29(2):158-64. https://doi.org/10.1177/1120672118785276
  3. Davies R, Watkins WJ, Kotecha S, Watts P. The presentation, clinical features, complications, and treatment of congenital dacryocystocele. Eye 2018; 32(3):522-6. https://doi.org/10.1038/eye.2017.235
  4. Foster JA, Carter KD, Durariraj VD, Kavanag MC, Korn BS, Nelson CC, et al. Basic and Clinical Science Course (BCSC), Section 7: Orbit, Eyelids and Lacrimal System. San Fransisco: American Academy of Ophthalmology; 2015.
  5. Schnall BM, Christian CJ. Conservative treatment of congenital dacryocele. J Pediatr Ophthalmol Strabismus 1996; 33(5):219-22.
  6. Becker BB. The treatment of congenital dacryocystocele. Am J Ophthalmol 2006; 142(5):835-8. https://doi.org/10.1016/j.ajo.2006.05.043
  7. Thakrar P, Chivate R, Choudhary R, Patkar D, Deshmukh S. Congenital Bilateral Dacryocystocele. Int J Heal Sci Res 2016; 6(3):329-35.
  8. Ali MJ, Psaltis AJ, Brunworth J, Naik MN, Wormald PJ. Congenital dacryocele with large intranasal cyst: Efficacy of cruciate marsupialization, adjunctive procedures, and outcomes. Ophthalmic Plast Reconstr Surg 2014; 30(4):346-51. https://doi.org/10.1097/IOP.0000000000000206
  9. Pujari A. Congenital dacryocystocele. BMJ Case Rep 2016; 2016:bcr2016218029. https://doi.org/10.1136/bcr-2016-218029
  10. Lorena SHT, Gonçalves ED, Silva JAF. Congenital dacryocystocele: Case report and treatment. Rev Bras Oftalmol 2014; 73(4):243-5.
  11. Raslan OA, Ozturk A, Pham N, Chang J, Strong EB, Bobinski M. A Comprehensive Review of Cross-Sectional Imaging of the Nasolacrimal Drainage Apparatus: What Radiologists Need to Know. Am J Roentgenol 2019; 213(6):1331-40. https://doi.org/10.2214/AJR.19.2150
  12. Mirza AA, Alsharif AF, Elmays OA, Marglani OA. Foreign body mimicking malignancy in acquired dacryocystocele. Clin Case Reports 2017; 5(3):296-9. https://doi.org/10.1002/ccr3.826
  13. Gendeh BS. Endoscopic dacryocystorhinostomy. In Tech Open 2018; 7(2):153-9. https://doi.org/10.5772/intechopen.81831
  14. Leatherbarrow B. Oculoplastic Surgery. 3rd Edition. Thieme Medical Publishers; 2020.
  15. Al-Qahtani AS. Primary endoscopic dacryocystorhinostomy with or without silicone tubing: a prospective randomized study. Am J Rhinol Allergy 2012; 26(4):332-4. https://doi.org/10.2500/ajra.2012.26.3789
  16. Saeed BMN. Endoscopic DCR without stents: Clinical guidelines and procedure. Eur Arch Otorhinolaryngol 2012; 269(2):545-9. https://doi.org/10.1007/s00405-011-1727-3
  17. Celenk F, Mumbuc S, Durucu C, Karatas ZA, Aytaç I, Baysal E, et al. Pediatric endonasal endoscopic dacryocystorhinostomy. Int J Pediatr Otorhinolaryngol 2013; 77(8):1259-62. https://doi.org/10.1016/j.ijporl.2013.05.004
  18. Sarbajna T, Takahashi Y, Regina M, Valencia P, Ana-magadia MG, Ishikawa E, et al. Dacryoendoscopy-assisted nasal endoscopic marsupialization for congenital dacryocystocele. Int J Pediatr Otorhinolaryngol 2018; 115:54-7. https://doi.org/10.1016/j.ijporl.2018.09.017
  19. Malacards. Human disease data base. 2020. Available at: https://www.malacards.org/card/chromosome_2q35_duplication_syndrome#:



DOI: https://doi.org/10.19106/JMedSci005304202110

Article Metrics

Abstract views : 1015 | views : 1555


Bookmark and Share


Copyright (c) 2021 Yunia Irawati, Alexander Krishna Ernanda, Florentina Priscilia, Retno Sulistyo Wardani

Creative Commons License
This work is licensed under a Creative Commons Attribution-NonCommercial 4.0 International License.